Table 1.

Positive NBS cases

Case no.Gene (MOI)VariantZygosityTRECsaPhenotype
RAG1 (AR) NM_000448.3: c.519del
p.(Glu174SerfsTer27) 
Homozygous SCID 
RAG1 (AR) NM_000448.3: c.1331C>T
p.(Ala444Val) 
Homozygous SCID 
RAG1 (AR) NM_000448.3: c.2095C>T
p.(Arg699Trp) and c.2974A>G
p.(Lys992Glu) 
Compound heterozygous SCID 
IL2RG (XL) NM_000206.3: c.298C>T
p.(Gln100Ter) 
Hemizygous SCID 
IL2RG (XL) NM_000206.3: c.190G>A
p.(Val64Met) 
Hemizygous SCID 
FOXN1 (AD/AR) NM_003593.3: c.831-2A>G
p.(?) 
Heterozygous >2 and ≤10 FOXN1 haploinsufficiency 
FOXN1 (AD/AR) NM_003593.3: c.143del
p.(Cys48SerfsTer254) 
Heterozygous >2 and ≤10 FOXN1 haploinsufficiency 
FOXN1 (AD/AR) NM_003593.3: c.1079T>C
p.(Leu360Pro) 
Heterozygous ≤2 FOXN1 haploinsufficiency 
RMRP (AR) NR_003051.3: n.147G>A and n.-32_1dup Compound heterozygous ≤2 Cartilage hair hypoplasia 
10 ATM (AR) NM_000051.4:c.5979_5983del
p.(Ser1993ArgfsTer23) and
c.7875_7876delinsGC
p.(Asp2625_Ala2626delinsGluPro) 
Compound heterozygous >2 and ≤10 Ataxia telangiectasia 
11 TBX1 (AD) TBX1 deletion Heterozygous ≤2 22q11.2 deletion syndrome 
12 TBX1 (AD) TBX1 deletion Heterozygous ≤2 22q11.2 deletion syndrome 
13 TBX1 (AD) TBX1 deletion Heterozygous >2 and ≤10 22q11.2 deletion syndrome 
14 TBX1 (AD) TBX1 deletion Heterozygous >2 and ≤10 22q11.2 deletion syndrome 
15 TBX1 (AD) TBX1 deletion Heterozygous >2 and ≤10 22q11.2 deletion syndrome 
52 TBX1 (AD) TBX1 deletion Heterozygous >2 and ≤10 Unknown 

AD, autosomal dominant; MOI, mode of inheritance. Detected variants, TREC results, and clinical phenotype of positive cases identified by second-tier NGS in the analyzed NBS samples (n total = 162).

a

Copies/3.2 mm DBS punch (ImmunoIVD).

or Create an Account

Close Modal
Close Modal