Table 2.

Immunological assessment

Initial assessmentP1 (7 yo)P2 (6 mo)P3 (11 yo)P4 (2 yo)P5 (6 yo)
FBC 
Lymphocytes/µl 780 (1,500–7,000) 1,080 (3,000–13500) 530 (1,200–5,200) 1,600 (6,000–9,000) 800 (1,500–6,500) 
Neutrophils/µl 7,510 (1,500–8,000) 3,280 (1,000–8,500) 2,480 (1,800–8,000) 1,900 (1,500–8,000) 9,860 (1,500–8,000) 
Eosinophils/µl 330 (100–800) 160 (100–300) 310 (100–800) 600 (200–1,000) 90 (40–400) 
Platelets/µl 109k (150k–450k) 318k (150k–450k) 142k (150k–450k) 327k (150k–400k) 478k (140k–400k) 
LSS 
CD3+ cells/µl 170 (1,352–3,275) 230 (3,764–6,289) 430 (930–3,477) 530 (852–5,333) 580 (1,200–2,600) 
CD4+ cells/µl 10 (776–1,815) 130 (2,093–4,769) 290 (576–1,891) 360 (516–3,448) 270 (650–1,500) 
CD8+ cells/µl 120 (366–1,171) 100 (720–1,271) 130 (261–1,189) 100 (188–1,805) 300 (370–1,100) 
CD4+CD45RA+CD27+ cells/µl 0 (424–1,393) 10 (1,748–4,201) 90 (264–1,484) NA NA 
CD8+CD45RA+CD27+ cells/µl 86 (175–730) 10 (564–1,040) 85 (94–986) NA NA 
CD16+CD56+ cells/µl 280 (106–1,348) 530 (237–1,146) 20 (109–1,021) 590 (138–1,759) 410 (100–480) 
CD19+ cells/µl 260 (157–725) 280 (896–2,316) 40 (173–1,194) 680 (232–1,637) 240 (270–860) 
TRECS/106 T cells Absent 1,028 (10th %: 15,337, median: 35,982) 7,797 (10th %: 8,538, median: 22,214) NA NA 
Spectratyping Abnormal Abnormal Abnormal NA NA 
PHA response Absent Absent Impaired Borderlinea Impaired 
IgG (g/liter) 12.50 (5.4–16.1) 2.75 (3–9) 4.64 (6–16) 15.2 (6–16) 9.0 (4.9–16.1) 
IgA (g/liter) 1.29 (0.7–2.5) 0.19 (0.15–0.7) 2.57 (0.8–2.8) 1.8 (0.8–2.8) 3.68 (0.50–2.4) 
IgM (g/liter) 0.63 (0.5–1.8) 0.08 (0.4–1.6) 0.47 (0.5–1.9) 0.3 (0.5–1.9) 0.37 (0.5–1.8) 
Vaccine responsesb Normal NA Normal Normal Normal 
POST-HCT P1 (14 years post; 24 yo) P2 (2 years post; 6 yo) P3 (10 years post; 32 yo)  P5 (6 mo post; 13 yo) 
T cell donor chimerism 41% 100% 91%  100% 
Lymphocytes/µl 1,001 (895–3,684) 2,110 (1,827–4,564) 1,102 (895–3,684)  930 (1,238–4,792) 
LSS      
CD3+ cells/µl 780 (564–2,935) 1,640 (1,352–3,275) 735 (564–2,935)  690 (930–3,477) 
CD4+ cells/µl 390 (207–1,900) 970 (776–1,815) 396 (207–1,900)  510 (576–1,891) 
CD8+ cells/µl 320 (160–1,103) 320 (366–1,171) 339 (160–1,103)  160 (261–1,189) 
TRECS/106 T cells 4,225 (10th %: NA; median: 4,120) 9,710 (10th %: 8,538, median: 22,214) 4,418c (10th %: NA, median: 4,120)  2,080 (10th %: NA, median: 15,284) 
Spectratyping Normal Normal Abnormalc  Improved 
PHA response Normal Normal Normal  Normal 
Initial assessmentP1 (7 yo)P2 (6 mo)P3 (11 yo)P4 (2 yo)P5 (6 yo)
FBC 
Lymphocytes/µl 780 (1,500–7,000) 1,080 (3,000–13500) 530 (1,200–5,200) 1,600 (6,000–9,000) 800 (1,500–6,500) 
Neutrophils/µl 7,510 (1,500–8,000) 3,280 (1,000–8,500) 2,480 (1,800–8,000) 1,900 (1,500–8,000) 9,860 (1,500–8,000) 
Eosinophils/µl 330 (100–800) 160 (100–300) 310 (100–800) 600 (200–1,000) 90 (40–400) 
Platelets/µl 109k (150k–450k) 318k (150k–450k) 142k (150k–450k) 327k (150k–400k) 478k (140k–400k) 
LSS 
CD3+ cells/µl 170 (1,352–3,275) 230 (3,764–6,289) 430 (930–3,477) 530 (852–5,333) 580 (1,200–2,600) 
CD4+ cells/µl 10 (776–1,815) 130 (2,093–4,769) 290 (576–1,891) 360 (516–3,448) 270 (650–1,500) 
CD8+ cells/µl 120 (366–1,171) 100 (720–1,271) 130 (261–1,189) 100 (188–1,805) 300 (370–1,100) 
CD4+CD45RA+CD27+ cells/µl 0 (424–1,393) 10 (1,748–4,201) 90 (264–1,484) NA NA 
CD8+CD45RA+CD27+ cells/µl 86 (175–730) 10 (564–1,040) 85 (94–986) NA NA 
CD16+CD56+ cells/µl 280 (106–1,348) 530 (237–1,146) 20 (109–1,021) 590 (138–1,759) 410 (100–480) 
CD19+ cells/µl 260 (157–725) 280 (896–2,316) 40 (173–1,194) 680 (232–1,637) 240 (270–860) 
TRECS/106 T cells Absent 1,028 (10th %: 15,337, median: 35,982) 7,797 (10th %: 8,538, median: 22,214) NA NA 
Spectratyping Abnormal Abnormal Abnormal NA NA 
PHA response Absent Absent Impaired Borderlinea Impaired 
IgG (g/liter) 12.50 (5.4–16.1) 2.75 (3–9) 4.64 (6–16) 15.2 (6–16) 9.0 (4.9–16.1) 
IgA (g/liter) 1.29 (0.7–2.5) 0.19 (0.15–0.7) 2.57 (0.8–2.8) 1.8 (0.8–2.8) 3.68 (0.50–2.4) 
IgM (g/liter) 0.63 (0.5–1.8) 0.08 (0.4–1.6) 0.47 (0.5–1.9) 0.3 (0.5–1.9) 0.37 (0.5–1.8) 
Vaccine responsesb Normal NA Normal Normal Normal 
POST-HCT P1 (14 years post; 24 yo) P2 (2 years post; 6 yo) P3 (10 years post; 32 yo)  P5 (6 mo post; 13 yo) 
T cell donor chimerism 41% 100% 91%  100% 
Lymphocytes/µl 1,001 (895–3,684) 2,110 (1,827–4,564) 1,102 (895–3,684)  930 (1,238–4,792) 
LSS      
CD3+ cells/µl 780 (564–2,935) 1,640 (1,352–3,275) 735 (564–2,935)  690 (930–3,477) 
CD4+ cells/µl 390 (207–1,900) 970 (776–1,815) 396 (207–1,900)  510 (576–1,891) 
CD8+ cells/µl 320 (160–1,103) 320 (366–1,171) 339 (160–1,103)  160 (261–1,189) 
TRECS/106 T cells 4,225 (10th %: NA; median: 4,120) 9,710 (10th %: 8,538, median: 22,214) 4,418c (10th %: NA, median: 4,120)  2,080 (10th %: NA, median: 15,284) 
Spectratyping Normal Normal Abnormalc  Improved 
PHA response Normal Normal Normal  Normal 

Laboratory age-matched reference ranges given in parentheses. Results that fall outside of their respective reference ranges are marked in bold. 10th %, 10th centile; FBC, full blood count; k, thousand; LSS; lymphocyte subsets; mo, months old; NA, not available; PHA, phytohemagglutinin; TRECs; TCR excision circles; yo, years old.

a

P4 proliferative response of 12,972 counts per minute (cpm) versus travel control 28,147 cpm (laboratory normal cut off at 12,500 cpm).

b

Assessed prior to the commencement of immunoglobulin replacement therapy.

c

Performed at 7 years post-HCT.

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